MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1530/ec-22-0240

Медицинская библиотека · Endocrine connections · 2023

Growth and disease burden in children with hypophosphatasia.

Högler Wolfgang, Linglart Agnès, Petryk Anna, Kishnani Priya S, Seefried Lothar, Fang Shona, Rockman-Greenberg Cheryl, Ozono Keiichi, Dahir Kathryn, Martos-Moreno Gabriel Ángel

СтатьяПеревод в очереди

Аннотация

OBJECTIVE

Hypophosphatasia, an inborn error of metabolism characterized by impaired bone mineralization, can affect growth. This study evaluated relationships between anthropometric parameters (height, weight, and body mass index) and clinical manifestations of hypophosphatasia in children.

DESIGN

Data from children (aged <18 years) with hypophosphatasia were analyzed from the observational Global Hypophosphatasia Registry.

METHODS

Anthropometric parameters were evaluated by age group (<2 years and ≥2 years) at assessment. The frequency of hypophosphatasia manifestations was compared between children with short stature (< percentile) and those with normal stature.

RESULTS

This analysis included 215 children (54.4% girls). Short stature presented in 16.1% of children aged <2 years and 20.4% of those aged ≥2 years at assessment. Among those with available data (n = 62), height was below the target height (mean: -0.66 standard deviations). Substantial worsening of growth (mean delta height z score: -1.45; delta weight z score: -0.68) occurred before 2 years of age, while in those aged ≥2 years, anthropometric trajectories were maintained (delta height z score: 0.08; delta weight z score: 0.13). Broad-ranging hypophosphatasia manifestations (beyond dental) were observed in most children.

CONCLUSIONS

Short stature was not a consistent characteristic of children with hypophosphatasia, but growth impairment was observed in those aged <2 years, indicating that hypophosphatasia might affect growth plate activity during infancy. In addition, a broad range of clinical manifestations occurred in those above and below the third percentile for height, suggesting that height alone may not accurately reflect hypophosphatasia disease burden and that weight is less affected than longitudinal growth.

Для цитирования: Högler Wolfgang, Linglart Agnès, Petryk Anna, Kishnani Priya S, Seefried Lothar, Fang Shona, Rockman-Greenberg Cheryl, Ozono Keiichi, Dahir Kathryn, Martos-Moreno Gabriel Ángel. Growth and disease burden in children with hypophosphatasia.. Endocrine connections. 2023. DOI: 10.1530/ec-22-0240.
Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.