MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1002/ajmg.a.38420

Медицинская библиотека · American journal of medical genetics. Part A · 2017

Prenatal diagnosis of femoral facial syndrome: Three case reports and literature review.

Luisin Marion, Chevreau Julien, Klein Céline, Naepels Philippe, Demeer Bénédicte, Mathieu-Dramard Michèle, Jedraszak Guillaume, Gondry-Jouet Catherine, Gondry Jean, Dieux-Coeslier Anne, Morin Gilles

Клинический случайСтатьяПеревод в очереди

Аннотация

Facial femoral syndrome (FFS) is a rare congenital abnormality, also known as femoral hypoplasia-unusual facies syndrome, characterized by variable degrees of femoral hypoplasia, associated with specific facial features. Other organ malformations are sometimes present. Most cases are sporadic, but rare family observations suggest genetic origin. However, no chromosomal or genetic abnormalities have ever been incriminated. We conducted a comprehensive literature review and added three new unreported observations. Through these 92 cases, authors aimed to determine sonographic signs that should direct towards diagnosis, and discuss potential genetic etiology. Diagnosis was suspected prenatally in 27.2% of cases, and maternal diabetes was found in 42.4% of patients. When fetal karyotype was available, it was normal in 97.1% of cases, but genomic variations of unknown significance were discovered in all three cases in which array comparative genomic hybridization (CGH) techniques were applied. Femoral affection defining FFS was hypoplasia in 78.3% of cases, agenesis in 12%, and both in 9.8%. Affection was bilateral in 84.8% of cases. Retrognathia was present in 65.2% of cases, cleft lip and/or palate in 63%, and other organ malformations in 53.3%. Intellectual development was normal in 79.2% of cases. Better prenatal recognition of this pathology, notably frequently associated malformations, should lead to a more precise estimation of functional prognosis. It seems likely that today's tendency to systematically employ array-CGH and exome/genome sequencing methods to investigate malformative sequences will allow the identification of a causal genetic abnormality in the near future.

Для цитирования: Luisin Marion, Chevreau Julien, Klein Céline, Naepels Philippe, Demeer Bénédicte, Mathieu-Dramard Michèle, Jedraszak Guillaume, Gondry-Jouet Catherine, Gondry Jean, Dieux-Coeslier Anne, Morin Gilles. Prenatal diagnosis of femoral facial syndrome: Three case reports and literature review.. American journal of medical genetics. Part A. 2017. DOI: 10.1002/ajmg.a.38420.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.