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DOI 10.3390/ijms23010438

Медицинская библиотека · International journal of molecular sciences · 2021

Multi-Omics Profiling in Marfan Syndrome: Further Insights into the Molecular Mechanisms Involved in Aortic Disease.

Verhagen Judith M A, Burger Joyce, Bekkers Jos A, den Dekker Alexander T, von der Thüsen Jan H, Zajec Marina, Brüggenwirth Hennie T, van der Sterre Marianne L T, van den Born Myrthe, Luider Theo M, van IJcken Wilfred F J, Wessels Marja W, Essers Jeroen, Roos-Hesselink Jolien W, van der Pluijm Ingrid, van de Laar Ingrid M B H, Brosens Erwin

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Аннотация

Thoracic aortic aneurysm is a potentially life-threatening disease with a strong genetic contribution. Despite identification of multiple genes involved in aneurysm formation, little is known about the specific underlying mechanisms that drive the pathological changes in the aortic wall. The aim of our study was to unravel the molecular mechanisms underlying aneurysm formation in Marfan syndrome (MFS). We collected aortic wall samples from FBN1 variant-positive MFS patients (n = 6) and healthy donor hearts (n = 5). Messenger RNA (mRNA) expression levels were measured by RNA sequencing and compared between MFS patients and controls, and between haploinsufficient (HI) and dominant negative (DN) FBN1 variants. Immunohistochemical staining, proteomics and cellular respiration experiments were used to confirm our findings. FBN1 mRNA expression levels were highly variable in MFS patients and did not significantly differ from controls. Moreover, we did not identify a distinctive TGF-β gene expression signature in MFS patients. On the contrary, differential gene and protein expression analysis, as well as vascular smooth muscle cell respiration measurements, pointed toward inflammation and mitochondrial dysfunction. Our findings confirm that inflammatory and mitochondrial pathways play important roles in the pathophysiological processes underlying MFS-related aortic disease, providing new therapeutic options.

Для цитирования: Verhagen Judith M A, Burger Joyce, Bekkers Jos A, den Dekker Alexander T, von der Thüsen Jan H, Zajec Marina, Brüggenwirth Hennie T, van der Sterre Marianne L T, van den Born Myrthe, Luider Theo M, van IJcken Wilfred F J, Wessels Marja W, Essers Jeroen, Roos-Hesselink Jolien W, van der Pluijm Ingrid, van de Laar Ingrid M B H, Brosens Erwin. Multi-Omics Profiling in Marfan Syndrome: Further Insights into the Molecular Mechanisms Involved in Aortic Disease.. International journal of molecular sciences. 2021. DOI: 10.3390/ijms23010438.

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