Human genetics · 2005
De novo t(7;10)(q33;q23) translocation and closely juxtaposed microdeletion in a patient with macrocephaly and developmental delay.
Клинический случайСтатьяПоддержка исследования: вне правительства СШАНазвание и аннотация: Перевод в очереди
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…
Ошибки и ограничения
История · было → стало
Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.
Yue Ying, Grossmann Baerbel, Holder Susan E, Haaf Thomas
Аннотация
We have applied FISH with fully integrated BACs and BAC subfragments assessed in the human genome sequence to a de novo t(7;10)(q33;q23) translocation in a patient with developmental delay and macrocephaly. The translocation breakpoints disrupt the SEC8L1 gene on chromosome 7 and the PTEN gene on chromosome 10. RT-PCR demonstrated chimeric transcripts containing the first 11 exons of SEC8L1 fused to exon 3 of PTEN. In addition to the balanced translocation, we found a 7-Mb deletion in the translocated part of chromosome 7 at 4-Mb distance of the translocation breakpoint. This microdeletion, which disrupts the PTN and TPK1 genes and deletes 29 bonafide genes and the T-cell receptor beta locus, arose in the paternal germline. The patient's phenotype may be caused by a dominant-negative effect of the SEC8L1-PTEN fusion protein and/or haploinsufficiency of the disrupted or deleted genes. Our study demonstrates that de novo translocations can be associated with microdeletions outside the breakpoint region(s), rendering the study and risk estimation of such breakpoints more complicated than previously assumed.
Предметные рубрики MeSH
Abnormalities, MultipleBase SequenceCarrier ProteinsChild, PreschoolChromosomes, Human, Pair 10Chromosomes, Human, Pair 7Developmental DisabilitiesFemaleGene DeletionHumansIn Situ Hybridization, FluorescenceMolecular Sequence DataPTEN PhosphohydrolasePhenotypePhosphoric Monoester HydrolasesReverse Transcriptase Polymerase Chain ReactionRisk FactorsScoliosisSkullTandem Repeat SequencesTranslocation, GeneticTumor Suppressor ProteinsVesicular Transport Proteins