MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1002/mgg3.556

Медицинская библиотека · Molecular genetics & genomic medicine · 2019

Interaction of germline variants in a family with a history of early-onset clear cell renal cell carcinoma.

Nicolas Emmanuelle, Demidova Elena V, Iqbal Waleed, Serebriiskii Ilya G, Vlasenkova Ramilia, Ghatalia Pooja, Zhou Yan, Rainey Kim, Forman Andrea F, Dunbrack Roland L, Golemis Erica A, Hall Michael J, Daly Mary B, Arora Sanjeevani

СтатьяПоддержка NIH: внешняя программаПоддержка исследования: вне правительства СШАПоддержка правительства СШАПеревод в очереди

Аннотация

BACKGROUND

Identification of genetic factors causing predisposition to renal cell carcinoma has helped improve screening, early detection, and patient survival.

METHODS

We report the characterization of a proband with renal and thyroid cancers and a family history of renal and other cancers by whole-exome sequencing (WES), coupled with WES analysis of germline DNA from additional affected and unaffected family members.

RESULTS

This work identified multiple predicted protein-damaging variants relevant to the pattern of inherited cancer risk. Among these, the proband and an affected brother each had a heterozygous Ala45Thr variant in SDHA, a component of the succinate dehydrogenase (SDH) complex. SDH defects are associated with mitochondrial disorders and risk for various cancers; immunochemical analysis indicated loss of SDHB protein expression in the patient's tumor, compatible with SDH deficiency. Integrated analysis of public databases and structural predictions indicated that the two affected individuals also had additional variants in genes including TGFB2, TRAP1, PARP1, and EGF, each potentially relevant to cancer risk alone or in conjunction with the SDHA variant. In addition, allelic imbalances of PARP1 and TGFB2 were detected in the tumor of the proband.

CONCLUSION

Together, these data suggest the possibility of risk associated with interaction of two or more variants.

Для цитирования: Nicolas Emmanuelle, Demidova Elena V, Iqbal Waleed, Serebriiskii Ilya G, Vlasenkova Ramilia, Ghatalia Pooja, Zhou Yan, Rainey Kim, Forman Andrea F, Dunbrack Roland L, Golemis Erica A, Hall Michael J, Daly Mary B, Arora Sanjeevani. Interaction of germline variants in a family with a history of early-onset clear cell renal cell carcinoma.. Molecular genetics & genomic medicine. 2019. DOI: 10.1002/mgg3.556.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.