MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1007/bf02983238

Медицинская библиотека · International journal of hematology · 2003

Mutational analysis of the WASP gene in 2 Korean families with Wiskott-Aldrich syndrome.

Jo Eun-Kyeong, Futatani Takeshi, Kanegane Hirokazu, Kubota Takeo, Lee Young-Ho, Jung Jin-A, Song Chang-Hwa, Park Jeong-Kyu, Nonoyama Shigeaki, Miyawaki Toshio

Клинический случайСтатьяПоддержка исследования: вне правительства СШАПеревод пока не подготовлен

Аннотация

Wiskott-Aldrich syndrome (WAS), an X-linked disorder characterized by thrombocytopenia with undersized platelets, eczema, and immune deficiency, is caused by mutations in the WASP gene. In this study, we investigated WASP gene mutations and WASP protein expression in 2 unrelated Korean WAS patients. Flow cytometry was used to evaluate WASP expression in lymphocytes. Two previously reported nonsense mutations (Arg211stop and Arg13stop) were identified in this study, a finding that suggested these codons are mutational hotspots. Both mothers showed normal WASP expression in flow cytometric analysis, even though they had heterozygotic patterning, which is indicative of carrier status. Furthermore, an X-chromosome inactivation assay revealed that these carrier mothers had skewed X inactivation. To our knowledge, this is the first report on molecular diagnosis of WAS in Korea. In addition, we detected normal WASP expression in lymphocytes from carrier mothers, a finding consistent with the data on skewed X inactivation.

Для цитирования: Jo Eun-Kyeong, Futatani Takeshi, Kanegane Hirokazu, Kubota Takeo, Lee Young-Ho, Jung Jin-A, Song Chang-Hwa, Park Jeong-Kyu, Nonoyama Shigeaki, Miyawaki Toshio. Mutational analysis of the WASP gene in 2 Korean families with Wiskott-Aldrich syndrome.. International journal of hematology. 2003. DOI: 10.1007/bf02983238.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.