Revista da Associacao Medica Brasileira (1992) · 2010
[Enzyme replacement therapy for mucopolysaccharidoses I, II and VI: recommendations from a group of Brazilian F experts].
СтатьяПоддержка исследования: вне правительства СШАНазвание и аннотация: Перевод пока не подготовлен
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…
Ошибки и ограничения
История · было → стало
Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.
Giugliani Roberto, Federhen Andressa, Muñoz Rojas Maria Verónica, Vieira Taiane Alves, Artigalás Osvaldo, Pinto Louise Lapagesse Carmargo, Azevedo Ana Cecília, Acosta Angelina Xavier, Bomfim Carmem, Lourenço Charles Marques, Kim Chong Ae, Horovitz Dafne, Souza Denize Bomfim, Norato Denise, Marinho Diane, Palhares Durval, Santos Emerson Santana, Ribeiro Erlane, Valadares Eugênia Ribeiro, Guarany Fábio, De Lucca Gisele Rosone, Pimentel Helena, Souza Isabel Neves de, Corrêa Neto Jordão, Fraga José Carlos, Góes José Eduardo, Cabral José Maria, Simeonato José, Llerena Juan Clinton, Jardim Laura Bannach, Giuliani Liane de Rosso, Silva Luiz Carlos Santana da, Santos Mara, Moreira Maria Angela, Kerstenetzky Marcelo, Ribeiro Márcia, Ruas Nicole, Barrios Patricia, Aranda Paulo, Honjo Rachel, Boy Raquel, Costa Ronaldo, Souza Carolina Fishinger Moura de, Alcântara Flavio F, Avilla Sylvio Gilberto A, Fagondes Simone, Martins Ana Maria
Аннотация
Mucopolysaccharidoses (MPS) are rare genetic diseases caused by deficiency of specific lysosomal enzymes that affect catabolism of glycosaminoglycans (GAG). Accumulation of GAG in various organs and tissues in MPS patients results in a series of signs and symptoms, producing a multisystemic condition affecting bones and joints, the respiratory and cardiovascular systems and many other organs and tissues, including in some cases, cognitive performance. So far, eleven enzyme defects that cause seven different types of MPS have been identified. Before introduction of therapies to restore deficient enzyme activity, treatment of MPS focused primarily on prevention and care of complications, still a very important aspect in the management of these patients. In the 80's treatment of MPS with bone marrow transplantation/hematopoietic stem cells transplantation (BMT/HSCT) was proposed and in the 90's, enzyme replacement therapy (ERT),began to be developed and was approved for clinical use in MPS I, II and VI in the first decade of the 21st century. The authors of this paper are convinced that a better future for patients affected by mucopolysaccharidoses depends upon identifying, understanding and appropriately managing the multisystemic manifestations of these diseases. This includes the provision of support measures (which should be part of regular multidisciplinary care of these patients) and of specific therapies. Although inhibition of synthesis of GAG and the recovery of enzyme activity with small molecules also may play a role in the management of MPS, the breakthrough is the currently available intravenous ERT. ERT radically changed the setting for treatment of mucopolysaccharidosis I, II and VI in the last decade., Benefits can even be extended soon to MPS IV A (ERT for this condition is already in clinical development), with prediction for treatment of MPS III A and the cognitive deficit in MPS II by administration of the enzyme directly into the central nervous system (CNS). A large number of Brazilian services, from all regions of the country, already have experience with ERT for MPS I, II and VI. This experience was gained not only by treating patients but also with the participation of some groups in clinical trials involving ERT for these conditions. Summing up the three types of MPS, more than 250 patients have already been treated with ERT in Brazil. The experience of professionals coupled to the data available in international literature, allowed us to elaborate this document, produced with the goal of bringing together and harmonize the information available for the treatment of these severe and progressive diseases, which, fortunately, are now treatable, a situation which bring new perspectives for Brazilian patients, affected by these conditions.