MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1007/s00381-022-05788-x

Медицинская библиотека · Child's nervous system : ChNS : official journal of the International Society for Pediatric Neurosurgery · 2022

Multisuture craniosynostosis: a case report of unusual presentation of chromosome 14q32 deletion.

Chaisrisawadisuk Sarut, Vatanavicharn Nithiwat, Khampalikit Inthira, Moore Mark H

Клинический случайСтатьяПеревод в очереди

Аннотация

Multisuture craniosynostosis is associated with a number of syndromes and underlying gene mutations. It is rarely caused by chromosome disorders. For the management, multisuture craniosynostosis raises concerns about abnormal head shape and risks of increased intracranial pressure in affected patients. Calvarial reconstruction to reshape the skull shape and expand the intracranial volume plays an essential role in correcting particular problems. Here, we report a 2-month-old female infant presenting with low birth weight, abnormal head shape, dysmorphic facies and pinnae, hypotonia, and feeding difficulty. Three-dimensional computed tomographic scans revealed left unicoronal and sagittal synostoses. Chromosome microarray analysis revealed de novo chromosome 14q32.12-q32.31 deletion. Among the deleted genes, YY1 and BCL11B are the most likely candidate genes causing craniosynostosis. Some clinical features of the patient are similar to Temple syndrome indicating that the deleted region is paternal in origin. In summary, this is a rare case of chromosome 14q32 deletion with multisuture craniosynostosis. We also report the multidisciplinary management and clinical outcomes after early cranial vault remodelling procedures.

Для цитирования: Chaisrisawadisuk Sarut, Vatanavicharn Nithiwat, Khampalikit Inthira, Moore Mark H. Multisuture craniosynostosis: a case report of unusual presentation of chromosome 14q32 deletion.. Child's nervous system : ChNS : official journal of the International Society for Pediatric Neurosurgery. 2022. DOI: 10.1007/s00381-022-05788-x.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.