Human genetics · 2019
Gene panel sequencing identifies a likely monogenic cause in 7% of 235 Pakistani families with nephrolithiasis.
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Amar Ali, Majmundar Amar J, Ullah Ihsan, Afzal Ayesha, Braun Daniela A, Shril Shirlee, Daga Ankana, Jobst-Schwan Tilman, Ahmad Mumtaz, Sayer John A, Gee Heon Yung, Halbritter Jan, Knöpfel Thomas, Hernando Nati, Werner Andreas, Wagner Carsten, Khaliq Shagufta, Hildebrandt Friedhelm
Аннотация
Nephrolithiasis (NL) affects 1 in 11 individuals worldwide and causes significant patient morbidity. We previously demonstrated a genetic cause of NL can be identified in 11-29% of pre-dominantly American and European stone formers. Pakistan, which resides within the Afro-Asian stone belt, has a high prevalence of nephrolithiasis (12%) as well as high rate of consanguinity (> 50%). We recruited 235 Pakistani subjects hospitalized for nephrolithiasis from five tertiary hospitals in the Punjab province of Pakistan. Subjects were surveyed for age of onset, NL recurrence, and family history. We conducted high-throughput exon sequencing of 30 NL disease genes and variant analysis to identify monogenic causative mutations in each subject. We detected likely causative mutations in 4 of 30 disease genes, yielding a likely molecular diagnosis in 7% (17 of 235) of NL families. Only 1 of 17 causative mutations was identified in an autosomal recessive disease gene. 10 of the 12 detected mutations were novel mutations (83%). SLC34A1 was most frequently mutated (12 of 17 solved families). We observed a higher frequency of causative mutations in subjects with a positive NL family history (13/109, 12%) versus those with a negative family history (4/120, 3%). Five missense SLC34A1 variants identified through genetic analysis demonstrated defective phosphate transport. We examined the monogenic causes of NL in a novel geographic cohort and most frequently identified dominant mutations in the sodium-phosphate transporter SLC34A1 with functional validation.
Предметные рубрики MeSH
AdolescentAdultAgedAllelesAnimalsChildChild, PreschoolCohort StudiesDNA Mutational AnalysisFamilyFemaleGene Expression ProfilingGenetic Association StudiesGenetic Predisposition to DiseaseGenotypeGeography, MedicalHigh-Throughput Nucleotide SequencingHumansInfantMaleMiddle AgedMutationNephrolithiasisPakistanSodium-Phosphate Cotransporter Proteins, Type IIaXenopus laevisYoung Adult