MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1016/j.cca.2019.10.031

Медицинская библиотека · Clinica chimica acta; international journal of clinical chemistry · 2019

α-Galactosidase A/lysoGb3 ratio as a potential marker for Fabry disease in females.

Baydakova G V, Ilyushkina A A, Moiseev S, Bychkov I O, Nikitina N V, Buruleva Т А, Zakharova E Y

СтатьяПеревод пока не подготовлен

Аннотация

Fabry disease (FD [MIM:301500]) is an X-linked lysosomal storage disorder caused by mutations in the GLA gene. Deficient activity of its product, lysosomal enzyme α-galactosidase A (α-Gal A), leads to excessive accumulation of glycosphingolipids in cells of multiple organs. The establishing of the diagnosis is challenge in female patients because of milder clinical manifestation and normal α-Gal A activity. The globotriaosylsphingosine (lysoGb3) is described as a more sensitive diagnostic biomarker for females with pathogenic mutation in the GLA gene. Thus, the aim of this study is to improve the biochemical diagnostic efficiency for FD in females. Here we report the α-Gal A/lysoGb3 ratio as the novel biochemical criteria for diagnosis of female patients with FD, using dried blood spots (DBS) as test samples. It showed 100% sensitivity in distinguishing our group of 35 female patients from control (n = 140). Whereas measurement of α-Gal A and lysoGb3 alone showed 8.6% and 74.4% respectively. A new approach of using the ratio of α-Gal A activity to lysoGb3 concentration in DBS may provide a more accurate screening tool for identification of FD females.

Для цитирования: Baydakova G V, Ilyushkina A A, Moiseev S, Bychkov I O, Nikitina N V, Buruleva Т А, Zakharova E Y. α-Galactosidase A/lysoGb3 ratio as a potential marker for Fabry disease in females.. Clinica chimica acta; international journal of clinical chemistry. 2019. DOI: 10.1016/j.cca.2019.10.031.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.