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DOI 10.1007/s10545-011-9444-z

Медицинская библиотека · Journal of inherited metabolic disease · 2012

Mucopolysaccharidosis: cardiologic features and effects of enzyme-replacement therapy in 24 children with MPS I, II and VI.

Brands Marion M M G, Frohn-Mulder Ingrid M, Hagemans Marloes L C, Hop Wim C J, Oussoren Esmee, Helbing Wim A, van der Ploeg Ans T

СтатьяПоддержка исследования: вне правительства СШАПеревод пока не подготовлен

Аннотация

We determined the cardiologic features of children with MPS I, II and VI, and evaluated the effect of enzyme-replacement therapy (ERT) on cardiac disease. Twenty-four children aged 1-18 years with MPS I, II or VI were prospectively evaluated with echocardiogram and electrocardiogram from the start of enzyme-replacement therapy up to 6 years of treatment. At start of therapy, 66% had abnormal cardiac geometric features. Left-ventricular mass index (LVMI) was increased in half of the patients, due mainly to concentric hypertrophy in MPS I and II and to eccentric hypertrophy in MPS VI. Regurgitation was most severe in a subgroup of young MPS VI patients (<5 years) at the mitral valve. At baseline, all patients had abnormal valves. The ECG showed no clear rhythm or conduction abnormalities; neither, in most patients, did it reflect the hypertrophy. After ERT, the LVMI Z-score normalized in 70% of the patients who had a Z-score > 2. LVMI Z-scores decreased significantly in patients with MPS I and MPS II (p = 0.04 and p = 0.032). Despite ERT, valve regurgitation increased in 60% of the patients. We conclude that all our MPS patients have cardiac abnormalities. The most severe cardiac disease was observed in a subgroup of young MPS VI patients. While ERT had an effect on LVMI and IVSd, it apparently had little or none on valve regurgitation.

Для цитирования: Brands Marion M M G, Frohn-Mulder Ingrid M, Hagemans Marloes L C, Hop Wim C J, Oussoren Esmee, Helbing Wim A, van der Ploeg Ans T. Mucopolysaccharidosis: cardiologic features and effects of enzyme-replacement therapy in 24 children with MPS I, II and VI.. Journal of inherited metabolic disease. 2012. DOI: 10.1007/s10545-011-9444-z.

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