MedElevator Войти в исследования
← Поиск публикаций

DOI 10.1515/jpem-2017-0397

Медицинская библиотека · Journal of pediatric endocrinology & metabolism : JPEM · 2018

Hypogammaglobulinemia and imaging features in a patient with infantile free sialic acid storage disease (ISSD) and a novel mutation in the SLC17A5 gene.

Žigman Tamara, Petković Ramadža Danijela, Lušić Mario, Zekušić Marija, Ninković Dorotea, Gardijan Danilo, Potočki Kristina, Omerza Lana, Beljan Lucija, Žarković Kamelija, Kerkhof Jennifer, Ljubojević Marija, de Sain-van der Velden Monique, Vuković Jurica, Fumić Ksenija, Sadiković Bekim, Barić Ivo

Клинический случайСтатьяПеревод пока не подготовлен

Аннотация

Background Infantile free sialic acid storage disease (ISSD) is a severe multisystemic disorder characterized by the accumulation of free sialic acid in lysosomes. Case presentation The patient presented prenatally with fetal ascites and large scrotal hernias, without pleural or pericardial effusion. During the infantile period, he was diagnosed with permanent isolated immunoglobulin G (IgG) hypogammaglobulinemia, which thus far has rarely been associated with ISSD. The analysis of the SLC17A5 gene revealed a novel homozygous 94 bp gene deletion. We further provide a detailed description of pre- and postnatal clinical and radiographic findings. Conclusions Fetal ascites could be the first sign of several lysosomal storage diseases (LSDs), including ISSD. The analysis of LSD gene panels is an effective approach to diagnosis in the case of non-specific symptoms and when specific biochemical tests are not easily available.

Для цитирования: Žigman Tamara, Petković Ramadža Danijela, Lušić Mario, Zekušić Marija, Ninković Dorotea, Gardijan Danilo, Potočki Kristina, Omerza Lana, Beljan Lucija, Žarković Kamelija, Kerkhof Jennifer, Ljubojević Marija, de Sain-van der Velden Monique, Vuković Jurica, Fumić Ksenija, Sadiković Bekim, Barić Ivo. Hypogammaglobulinemia and imaging features in a patient with infantile free sialic acid storage disease (ISSD) and a novel mutation in the SLC17A5 gene.. Journal of pediatric endocrinology & metabolism : JPEM. 2018. DOI: 10.1515/jpem-2017-0397.

Предметные рубрики MeSH

Подготовка и перевод публикации
Обработка статьи · этапы, ошибки и управление
Загрузка состояния…

История · было → стало

Состояние обновляется каждые 5 секунд, пока блок открыт. Процент показывается только там, где известен объём работы. Пауза останавливает продолжение этапа; текущий запрос к источнику может завершиться.

Тип публикации указан по данным источника. Уровень доказательности автоматически не присваивается.