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DOI 10.1038/s10038-019-0693-2

Медицинская библиотека · Journal of human genetics · 2019

A novel POC1A variant in an alternatively spliced exon causes classic SOFT syndrome: clinical presentation of seven patients.

Al-Kindi Adila, Al-Shehhi Maryam, Westenberger Ana, Beetz Christian, Scott Patrick, Brandau Oliver, Abbasi-Moheb Lia, Yüksel Zafer, Bauer Peter, Rolfs Arndt, Grüning Nana-Maria

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Аннотация

Biallelic pathogenic variants in POC1A are ultra rare. They have been reported in 13 families as causing either Short stature, Onychodysplasia, Facial dysmorphism, and hypoTrichosis (SOFT) syndrome, or a milder partially overlapping phenotype, variant POC1A-related syndrome. This pleiotropic effect is likely precipitated by the variant's location and respective affected protein domain. Here, we describe seven patients from two consanguineous Omani families with classic SOFT syndrome and a novel homozygous POC1A variant (c.64G>T; p.(Val22Phe)), which is the first one described for the alternative exon 2. This result refines the POC1A mutational spectrum relevant for exertion of the described pleiotropic effect. Furthermore, six of our patients experienced recurrent mild to severe respiratory difficulties that have not been previously reported for SOFT syndrome and may be an underdiagnosed or a genotype-specific complication that warrants attention in future studies. Thus, our study unravels new aspects of the genotype-phenotype correlation suggested by previous reports.

Для цитирования: Al-Kindi Adila, Al-Shehhi Maryam, Westenberger Ana, Beetz Christian, Scott Patrick, Brandau Oliver, Abbasi-Moheb Lia, Yüksel Zafer, Bauer Peter, Rolfs Arndt, Grüning Nana-Maria. A novel POC1A variant in an alternatively spliced exon causes classic SOFT syndrome: clinical presentation of seven patients.. Journal of human genetics. 2019. DOI: 10.1038/s10038-019-0693-2.

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